147 research outputs found
Hereditary palmoplantar keratoderma - phenotypes and mutations in 64 patients
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- Publication venue
- Publication date
- 01/01/2021
- Field of study
Background Hereditary palmoplantar keratodermas (PPK) represent a heterogeneous group of rare skin disorders with epidermal hyperkeratosis of the palms and soles, with occasional additional manifestations in other tissues. Mutations in at least 69 genes have been implicated in PPK, but further novel candidate genes and mutations are still to be found. Objectives To identify mutations underlying PPK in a cohort of 64 patients. Methods DNA of 48 patients was analysed on a custom-designed in-house panel for 35 PPK genes, and 16 patients were investigated by a diagnostic genetic laboratory either by whole-exome sequencing, gene panels or targeted single-gene sequencing. Results Of the 64 PPK patients, 32 had diffuse (50%), 19 focal (30%) and 13 punctate (20%) PPK. None had striate PPK. Pathogenic mutations in altogether five genes were identified in 31 of 64 (48%) patients, the majority (22/31) with diffuse PPK. Of them, 11 had a mutation in AQP5, five in SERPINB7, four in KRT9 and two in SLURP1. AAGAB mutations were found in nine punctate PPK patients. New mutations were identified in KRT9 and AAGAB. No pathogenic mutations were detected in focal PPK. Variants of uncertain significance (VUS) in PPK-associated and other genes were observed in 21 patients that might explain their PPK. No suggestive pathogenic variants were found for 12 patients. Conclusions Diffuse PPK was the most common (50%) and striate PPK was not observed. We identified pathogenic mutations in 48% of our PPK patients, mainly in five genes: AQP5, AAGAB, KRT9, SERPINB7 and SLURP1.Peer reviewe
X-ray emission from the Sombrero galaxy: discrete sources
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- Villella I
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- Vogel H
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- Vorobiev I
- Vorobyev A
- Voutilainen M
- Wagner P
- Wagner SR
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- Wakefield S
- Wallny R
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- Waltenberger W
- Walzel G
- Wan Z
- Wang D
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- Wang X
- Wang Z
- Warchol J
- Ward S
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- Weinberg M
- Weinberger M
- Wendland L
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- Weng Y
- Wenger EA
- Werner JS
- Wetzel J
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- Whyntie T
- Wickens J
- Wickramage N
- Widl E
- Wigmans R
- Wilken R
- Wilkinson R
- Williams G
- Willmott C
- Wimpenny S
- Winn D
- Winstrom L
- Wissing C
- Wittich P
- Wittmer B
- Wohri HK
- Wolf R
- Womersley WJ
- Won S
- Wood D
- Wood JS
- Worm SD
- Wright D
- Wrochna G
- Wu JH
- Wu W
- Wulz CE
- Wurthwein F
- Wyslouch B
- Xiao H
- Xie S
- Xu M
- Yagil A
- Yan M
- Yang F
- Yang M
- Yang M
- Yang Y
- Yang ZC
- Yazgan E
- Yelton J
- Yetkin T
- Yi K
- Yildirim E
- Yilmaz Y
- Yohay R
- Yoo HD
- Yoon AS
- York A
- Yu I
- Yu SS
- Yumiceva F
- Yun JC
- Zabel J
- Zabi A
- Zablocki J
- Zaganidis N
- Zakaria M
- Zalewski P
- Zanetti M
- Zang J
- Zang SL
- Zarubin A
- Zatserklyaniy A
- Zeinali M
- Zeise M
- Zeuner WD
- Zeyrek M
- Zhang J
- Zhang L
- Zhang Z
- Zheng Y
- Zhokin A
- Zhu B
- Zhu RY
- Zhukov V
- Zhukova V
- Ziebarth EB
- Ziegler J
- Zielinski M
- Zito G
- Zoeller MH
- Zorbilmez C
- Zotto P
- Zou W
- Zumerle G
- Zuranski A
- Publication venue
- 'IOP Publishing'
- Publication date
- 01/01/2010
- Field of study
We present a study of discrete X-ray sources in and around the
bulge-dominated, massive Sa galaxy, Sombrero (M104), based on new and archival
Chandra observations with a total exposure of ~200 ks. With a detection limit
of L_X = 1E37 erg/s and a field of view covering a galactocentric radius of ~30
kpc (11.5 arcminute), 383 sources are detected. Cross-correlation with Spitler
et al.'s catalogue of Sombrero globular clusters (GCs) identified from HST/ACS
observations reveals 41 X-rays sources in GCs, presumably low-mass X-ray
binaries (LMXBs). We quantify the differential luminosity functions (LFs) for
both the detected GC and field LMXBs, whose power-low indices (~1.1 for the
GC-LF and ~1.6 for field-LF) are consistent with previous studies for
elliptical galaxies. With precise sky positions of the GCs without a detected
X-ray source, we further quantify, through a fluctuation analysis, the GC LF at
fainter luminosities down to 1E35 erg/s. The derived index rules out a
faint-end slope flatter than 1.1 at a 2 sigma significance, contrary to recent
findings in several elliptical galaxies and the bulge of M31. On the other
hand, the 2-6 keV unresolved emission places a tight constraint on the field
LF, implying a flattened index of ~1.0 below 1E37 erg/s. We also detect 101
sources in the halo of Sombrero. The presence of these sources cannot be
interpreted as galactic LMXBs whose spatial distribution empirically follows
the starlight. Their number is also higher than the expected number of cosmic
AGNs (52+/-11 [1 sigma]) whose surface density is constrained by deep X-ray
surveys. We suggest that either the cosmic X-ray background is unusually high
in the direction of Sombrero, or a distinct population of X-ray sources is
present in the halo of Sombrero.Comment: 11 figures, 5 tables, ApJ in pres
Trends in the use of antiasthmatic medications in Morocco (1999â2010)
- Author
- A Cuerq
- A Sommet
- A Vergnenègre
- AP Greening
- B Abou-AtmĂŠ
- DC Yan
- DH Smith
- E Von Mutius
- ED Bateman
- F Coignard
- G Viens
- HAS
- High Authority for Health (HAS)
- High Commission of Planning-HCP
- I Carvajal-UrueĂąa
- I Urrutia
- JC Pujet
- KB Weiss
- L Com-Ruelle
- L GarcĂa-Marcos
- M Masoli
- MI Asher
- N AĂŻt-Khaled
- N AĂŻt-Khaled
- P Godard
- PJ Barnes
- PM OâByrne
- PW Ind
- R Beasley
- RA Pauwels
- S Shrewsbury
- SecrĂŠtariat gĂŠnĂŠral du gouvernement
- SecrĂŠtariat gĂŠnĂŠral du gouvernement
- Swiss Group for Pediatric Pneumology work (SAPP)
- WHO Collaborating Centre for Drug Statistics Methodology
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- Field of study
Study of B Meson Production in p plus Pb Collisions at root s(NN)=5.02 TeV Using Exclusive Hadronic Decays
- Author
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- Publication date
- 01/01/2015
- Field of study
Peer reviewe
Transverse-momentum and pseudorapidity distributions of charged hadrons in pp collisions at âs=7 TeV
- Author
- Abbaneo D
- Abbiendi G
- Abbrescia M
- Abdullin S
- Acosta D
- Acosta JG
- Acosta MV
- Actis O
- Adam N
- Adam W
- Adams MR
- Adams T
- Adiguzel A
- Adler V
- Adzic P
- Agostino L
- Agram JL
- Aguilar-Benitez M
- Ahmad M
- Ahmad WH
- Ahmed I
- Ahuja S
- Akchurin N
- Akgun B
- Akgun U
- Akin IV
- Alagoz E
- Albajar C
- Albayrak EA
- Albergo S
- Albrow M
- Alexander J
- Aliev T
- Allfrey P
- Almeida N
- Altsybeev I
- Alver B
- Alverson G
- Alves GA
- Amapane N
- Ambroglini F
- Amsler C
- Anagnostou G
- Anastassov A
- Anderson J
- Anderson M
- Andrea J
- Andreev V
- Andreev V
- Andreev Y
- Andrews W
- Anghel IM
- Antonelli L
- Antunovic Z
- Apanasevich L
- Apollinari G
- Appelt E
- Aranyi A
- Arce P
- Arcidiacono R
- Arenton MW
- Arfaei H
- Argiro S
- Arisaka K
- Arneodo M
- Asaadi J
- Asghar MI
- Askew A
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- Atac M
- Atramentov O
- Attikis A
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- Autermann C
- Avery P
- Avetisyan A
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- Azzurri P
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- Babb J
- Bacchetta N
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- Baden D
- Baesso P
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- Bagliesi G
- Baillon P
- Bainbridge R
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- Yetkin T
- Yi K
- Yilmaz Y
- Yohay R
- Yoo HD
- Yoon AS
- York A
- Yu I
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- Yumiceva F
- Yun JC
- Zabi A
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- Zaganidis N
- Zakaria M
- Zalewski P
- Zanetti M
- Zang SL
- Zarubin A
- Zatzerklyaniy A
- Zeidler C
- Zeinali M
- Zeise M
- Zennamo J
- Zeuner WD
- Zeyrek M
- Zhang J
- Zhang Z
- Zheng Y
- Zhokin A
- Zhu B
- Zhu RY
- Zhukov V
- Zhukova V
- Ziebarth EB
- Ziegler J
- Zielinski M
- Zinonos Z
- Zito G
- Zoeller MH
- Zorbilmez C
- Zumerle G
- Zuranski A
- Publication venue
- 'American Physical Society (APS)'
- Publication date
- 01/01/2010
- Field of study
This is the pre-print version of the Published Article which can be accessed from the link below.Charged-hadron transverse-momentum and pseudorapidity distributions in proton-proton collisions at âs=7ââTeV are measured with the inner tracking system of the CMS detector at the LHC. The charged-hadron yield is obtained by counting the number of reconstructed hits, hit pairs, and fully reconstructed charged-particle tracks. The combination of the three methods gives a charged-particle multiplicity per unit of pseudorapidity dNch/dΡ||Ρ|<0.5=5.78Âą0.01(stat)Âą0.23(syst) for non-single-diffractive events, higher than predicted by commonly used models. The relative increase in charged-particle multiplicity from âs=0.9 to 7 TeV is [66.1Âą1.0(stat)Âą4.2(syst)]%. The mean transverse momentum is measured to be 0.545Âą0.005(stat)Âą0.015(syst)ââGeV/c. The results are compared with similar measurements at lower energies
Indications of suppression of excited ÎĽ states in Pb-Pb collisions at âsNN = 2.76TeV
- Author
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- Zalewski P
- Zanetti M
- Zang J
- Zang SL
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- Zeinali M
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- Zennamo J
- Zeuner WD
- Zeyrek M
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- Zhang Z
- Zheng Y
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- Zhu B
- Zhu RY
- Zhukov V
- Zhukova V
- Ziebarth EB
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- Zielinski M
- Zito G
- Zoeller MH
- Zotto P
- Zou W
- Zumerle G
- Zuranski A
- Publication venue
- 'American Physical Society (APS)'
- Publication date
- 01/01/2011
- Field of study
This is the pre-print version of the Published Article which can be accessed from the link below.A comparison of the relative yields of ÎĽ resonances in the Îź+Îź- decay channel in Pb-Pb and pp collisions at a center-of-mass energy per nucleon pair of 2.76 TeV is performed with data collected with the CMS detector at the LHC. Using muons of transverse momentum above 4ââGeV/c and pseudorapidity below 2.4, the double ratio of the ÎĽ(2S) and ÎĽ(3S) excited states to the ÎĽ(1S) ground state in Pb-Pb and pp collisions, [ÎĽ(2S+3S)/ÎĽ(1S)]Pb-Pb/[ÎĽ(2S+3S)/ÎĽ(1S)]pp, is found to be 0.31-0.15+0.19(stat)Âą0.03(syst). The probability to obtain the measured value, or lower, if the true double ratio is unity, is calculated to be less than 1%
Search for supersymmetry in events with b jets and missing transverse momentum at the LHC
- Author
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- Yilmaz Y
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- Zumerle G
- Zuranski A
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- 01/01/2011
- Field of study
A search for supersymmetry is presented using a sample of events with b jets and missing transverse momentum. The search uses a data sample of proton-proton collisions at a centre-of-mass energy of 7TeV, corresponding to an integrated luminosity of 35 pb(-1), collected with the CMS detector. A total of 0.33(-0.33)(+0.43) (stat.) +/- 0.13 (syst.) events is predicted, using control samples in the data, to arise from standard model processes, and one event is observed in the data. Upper limits are set at the 95% confidence level on the cross sections of benchmark supersymmetric models
Long-range and short-range dihadron angular correlations in central PbPb collisions at âsNN=2.76 TeV
- Author
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- Metson S
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- Zoeller MH
- Zorbilmez C
- Zou W
- Zuranski A
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- 01/01/2011
- Field of study
This is the pre-print version of the Published Article, which can be accessed from the link below.First measurements of dihadron correlations for charged particles are presented
for central PbPb collisions at a nucleon-nucleon center-of-mass energy of 2.76TeV over a broad range in relative pseudorapidity ( ) and the full range of relative azimuthal angle ( ). The data were collected with the CMS detector, at the LHC. A broadening of the away-side ( ) azimuthal correlation is observed at all , as compared to the measurements in pp collisions. Furthermore, long-range dihadron correlations in are observed for particles with similar values. This phenomenon, also known as the \ridge",
persists up to at least j j = 4. For particles with transverse momenta (pT) of 2-4 GeV/c, the ridge is found to be most prominent when these particles are correlated with particles of pT = 2-6 GeV/c, and to be much reduced when paired with particles of pT = 10-12 GeV/c
Measurement of the t(t)over-bar production cross section in pp collisions at root s=7 TeV in dilepton final states containing a tau
- Author
- Abbaneo D
- Abbiendi G
- Abbrescia M
- Abdulsalam A
- Adam W
- Adiguzel A
- Adler Volker
- Adzic P
- Agram JL
- Aguilar-Benitez M
- Aguilo E
- Ahmad M
- Ahmad WH
- Ahuja S
- Akin IV
- Albajar C
- Albergo S
- Alda WL
- Aliev T
- Almeida N
- Alves GA
- Amapane N
- Amsler C
- Anagnostou G
- Andrea J
- Andreev V
- Andreev Y
- Anjos TS
- Antunes JR
- Antunovic Z
- Arce P
- Arcidiacono R
- Arfaei H
- Argiro S
- Arneodo M
- Asawatangtrakuldee C
- Asghar MI
- Assran Y
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- Ungaro D
- Urscheler C
- Uvarov L
- Uzunian A
- Valencia FV
- Van Doninck W
- Van Haevermaet H
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- Willmott C
- Wissing C
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- Wohri HK
- Worm SD
- Wrochna G
- Wulz CE
- Xiao H
- Xu M
- Yazgan Efe
- Yu I
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- Zabi A
- Zaganidis Nikolaos
- Zalewski P
- Zang J
- Zarubin A
- Zeinali M
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- Zhangv Z
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- Zhu B
- Zhukov V
- Ziebarth EB
- Zito G
- Zotto P
- Zou W
- Zumerle G
- Publication venue
- 'American Physical Society (APS)'
- Publication date
- 01/01/2012
- Field of study
The top quark pair production cross section is measured in dilepton events with one electron or muon, and one hadronically decaying tau lepton from the decay t (t) over bar -> (l nu(l))((sic)(h)nu((sic)))b (b) over bar, (l = e, mu). The data sample corresponds to an integrated luminosity of 2.0 fb(-1) for the electron channel and 2.2 fb(-1) for the muon channel, collected by the CMS detector at the LHC. This is the first measurement of the t (t) over bar cross section explicitly including tau leptons in proton- proton collisions at root s = 7 TeV. The measured value sigma(t (t) over bar) = 143 +/- 14(stat) +/- 22(syst) +/- 3(lumi) pb is consistent with the standard model predictions
Search for supersymmetry in pp collisions at 7 TeV in events with jets and missing transverse energy
- Author
- Abbaneo D
- Abbiendi G
- Abbrescia M
- Abdullin S
- Acosta D
- Acosta JG
- Acosta MV
- Adam N
- Adam W
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- Yilmaz Y
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- Yun JC
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- Zabi A
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- Zaganidis N
- Zakaria M
- Zalewski P
- Zanetti M
- Zang J
- Zang SL
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- Zeinali M
- Zeise M
- Zeuner WD
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- Zhang Z
- Zheng Y
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- Zhu B
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- Ziebarth EB
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- Zumerle G
- Zuranski A
- Publication venue
- Elsevier
- Publication date
- 01/01/2011
- Field of study
This is the Pre-print version of the Article. The official published version of the paper can be accessed from the link below - Copyright @ 2011 ElsevierA search for supersymmetry with R-parity conservation in proton-proton collisions at a centre-of-mass energy of 7 TeV is presented. The data correspond to an integrated luminosity of 35 inverse picobarns collected by the CMS experiment at the LHC. The search is performed in events with jets and significant missing transverse energy, characteristic of the decays of heavy, pair-produced squarks and gluinos. The primary background, from standard model multijet production, is reduced by several orders of magnitude to a negligible level by the application of a set of robust kinematic requirements. With this selection, the data are consistent with the standard model backgrounds, namely t t-bar, W + jet and Z + jet production, which are estimated from data control samples. Limits are set on the parameters of the constrained minimal supersymmetric extension of the standard model. These limits extend those set previously by experiments at the Tevatron and LEP colliders.This work is supported by FMSR (Austria); FNRS and FWO (Belgium); CNPq, CAPES, FAPERJ, and FAPESP (Brazil); MES (Bulgaria); CERN; CAS, MoST, and NSFC (China); COLCIENCIAS (Colombia); MSES (Croatia); RPF (Cyprus); Academy of Sciences and NICPB (Estonia); Academy of Finland, ME, and HIP (Finland); CEA and CNRS/IN2P3 (France); BMBF, DFG, and HGF (Germany); GSRT (Greece); OTKA and NKTH (Hungary); DAE and DST (India); IPM (Iran); SFI (Ireland); INFN (Italy); NRF and WCU (Korea); LAS (Lithuania); CINVESTAV, CONACYT,
SEP, and UASLP-FAI (Mexico); PAEC (Pakistan); SCSR (Poland); FCT (Portugal); JINR (Armenia, Belarus, Georgia, Ukraine, Uzbekistan); MST and MAE (Russia); MSTD (Serbia); MICINN and CPAN (Spain); Swiss Funding Agencies (Switzerland); NSC (Taipei); TUBITAK and TAEK (Turkey); STFC (United Kingdom); DOE and NSF (USA)
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