Congenital absence or rudiment major salivary glands, especially of the parotid glands, are a rare entity. Aplasia of
parotid glands has been described alone or in association with abnormalities of other salivary glands, first branchial
arch developmental disturbances and other congenital anomalies such as lacrimoauriculodentodigital syndrome,
mandibulofacial dysostosis and ectodermal dysplasia. Absence is most commonly unilateral, and may be associated
with accessory or rudimentary glandular tissue. There are several reported cases of isolated patulous Stensen’s duct
causing air insufflations in the glands and recurrent parotid gland enlargement. However, in the literature there is
no reported case of association of rudimentary parotid gland with a patulous Stensen’s duct. This paper aims at
reporting an interesting and unusual presentation of unilateral imperfectly developed parotid gland with a distended
Stensen’s duct in a five year old mentally challenged girl who presented with an unintentional habit of blowing out
cheeks several times in a day resulting in air insufflations and recurrent parotid swellin
