4 research outputs found
Massive Hemoptysis due to Right Inferior Phrenic Artery-to-Right Pulmonary Artery Fistula in the Right Middle Lobe of the Lung
- Publication venue
- 'Japanese Society of Internal Medicine'
- Publication date
- 01/01/2017
- Field of study
TTC39B deficiency stabilizes LXR reducing both atherosclerosis and steatohepatitis
- Author
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- 14/07/2016
- Field of study
Cellular mechanisms that mediate steatohepatitis, an increasingly prevalent condition in the Western world for which no therapies are available, are poorly understood. Despite the fact that its synthetic agonists induce fatty liver, the liver X receptor (LXR) transcription factor remains a target of interest because of its anti-atherogenic, cholesterol removal, and anti-inflammatory activities. Here we show that tetratricopeptide repeat domain protein 39B (Ttc39b, C9orf52) (T39), a high-density lipoprotein gene discovered in human genome-wide association studies, promotes the ubiquitination and degradation of LXR. Chow-fed mice lacking T39 (T39(-/-)) display increased high-density lipoprotein cholesterol levels associated with increased enterocyte ATP-binding cassette transporter A1 (Abca1) expression and increased LXR protein without change in LXR messenger RNA. When challenged with a high fat/high cholesterol/bile salt diet, T39(-/-) mice or mice with hepatocyte-specific T39 deficiency show increased hepatic LXR protein and target gene expression, and unexpectedly protection from steatohepatitis and death. Mice fed a Western-type diet and lacking low-density lipoprotein receptor (Ldlr(-/-)T39(-/-)) show decreased fatty liver, increased high-density lipoprotein, decreased low-density lipoprotein, and reduced atherosclerosis. In addition to increasing hepatic Abcg5/8 expression and limiting dietary cholesterol absorption, T39 deficiency inhibits hepatic sterol regulatory element-binding protein 1 (SREBP-1, ADD1) processing. This is explained by an increase in microsomal phospholipids containing polyunsaturated fatty acids, linked to an LXRα-dependent increase in expression of enzymes mediating phosphatidylcholine biosynthesis and incorporation of polyunsaturated fatty acids into phospholipids. The preservation of endogenous LXR protein activates a beneficial profile of gene expression that promotes cholesterol removal and inhibits lipogenesis. T39 inhibition could be an effective strategy for reducing both steatohepatitis and atherosclerosis
TTC39B deficiency stabilizes LXR reducing both atherosclerosis and steatohepatitis
- Author
- AK Walker
- AL Wu
- Alan R. Tall
- BD Hegarty
- Carrie L. Welch
- CJ Willer
- D Hishikawa
- Daniel J. Rader
- DE Kleiner
- DF Vatner
- DK Spady
- EG Bligh
- Emi Yakushiji
- G Lo Sasso
- G Musso
- Gilbert Di Paolo
- H Tomoyori
- HC Stary
- HL Kammoun
- Ikuyo Ichi
- J Iqbal
- J McNeish
- Jahangir Iqbal
- Jay H. Lefkowitch
- JJ Repa
- JL Collins
- Joanne Hsieh
- K Anwar
- L Yu
- Liana Tascau
- LR Brunham
- M Boergesen
- M Lehrke
- M. Mahmood Hussain
- Marit Westerterp
- Masahiro Koseki
- Matthew M. Molusky
- MJ Gijbels
- N Matsuzawa
- N Perreault
- N Zelcer
- P Costet
- RB Chan
- Robin B. Chan
- S Dzeletovic
- S Romeo
- Sandra Abramowicz
- Shizuya Yamashita
- Shunichi Takiguchi
- SJ Bensinger
- TM Teslovich
- VC Hannah
- X Rong
- Y Huang
- Y Zhang
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- Field of study
Listing of Protein Spectra
- Author
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- U Weser
- U Weser
- UE Handschin
- V Gonzales-Prevatt
- V Harisdangkul
- V Krasnobajeu
- V Larraga
- V Massey
- V Massey
- V Redkar
- V Scardi
- VA Eterovic
- VA Leonenko
- VA Rasskazov
- VB Yanushauskaite
- VF Kalb
- VG Neef
- VG Tumanyan
- VI Ivanov
- VK Shah
- VM Kochkina
- VP Miroshnichenko
- VP Pigiet
- VP Piriet
- VR Naik
- VS Sharma
- VS Zolotova
- VT Aikazyan
- VT Aikazyan
- VT Aikazyan
- VV Mesyanzhinov
- VV Moslov
- W Ardelt
- W Birchmeier
- W Birchmeier
- W Byers
- W Duntze
- W Junge
- W Kufer
- W Kunzer
- W Leicht
- W Levin
- W Levin
- W Levin
- W Mori
- W Scheler
- W Sebald
- W Strider
- W Tischer
- WA Bulen
- WA Robison
- WB Im
- WB Southerland
- WB Whitman
- WB Whitten
- WC Mccubbin
- WC Merrick
- WD Behnske
- WD Hewson
- WD Hewson
- WD Horrocks
- WF Cleere
- WF Line
- WF Swain
- WFHM Mommaerts
- WG Zumft
- WG Zumft
- WG Zumft
- WH Bannister
- WH Bannister
- WH Bishop
- WH Wu
- WJ Chang
- WJ Grip
- WJ Haas
- WJ Haas
- WJ Ray
- WJ Wallace
- WJ Wallace
- WJ Wallace
- WK Liu
- WL Hughes
- WL Muth
- WM Awad
- WM Moore
- WR Browett
- WR Carper
- WR Fisher
- WR Heineman
- WR Holmquist
- WR Melander
- WR Richards
- WR Richards
- WR Veatch
- WR Waud
- WR Waud
- WS Hancock
- WS Pierpoint
- WS Pierpoint
- WT Butler
- WT Morgan
- WT Morgan
- WT Perrie
- WV Sweeney
- WV Sweeney
- WV Sweeney
- WW Fish
- WW Ward
- WY Huang
- Y
- Y Atsuta
- Y Atsuta
- Y Beaux
- Y Beuzard
- Y Degani
- Y Fukumori
- Y Furusawa
- Y Hatefi
- Y Hayashi
- Y Hayashi
- Y Hayashi
- Y Henry
- Y Henry
- Y Ichikawa
- Y Igarashi
- Y Imai
- Y Imai
- Y Imai
- Y Imai
- Y Imai
- Y Ishida
- Y Itoh
- Y Kanai
- Y Kato
- Y Kurono
- Y Matsushita
- Y Miyake
- Y Morikawa
- Y Morino
- Y Morino
- Y Morino
- Y Morita
- Y Morita
- Y Motokawa
- Y Muto
- Y Nagi
- Y Nakagawa
- Y Nakagawa
- Y Nakamura
- Y Nisimoto
- Y Nisimoto
- Y Ohta
- Y Ohta
- Y Ohta
- Y Ohta
- Y Orii
- Y Orii
- Y Orii
- Y Ota
- Y Peled
- Y Sakagami
- Y Sakaki
- Y Sanada
- Y Sawada
- Y Schechter
- Y Schechter
- Y Seki
- Y Shichida
- Y Shioi
- Y Shioi
- Y Shioi
- Y Stefanovsky
- Y Sugimura
- Y Sugimura
- Y Sugita
- Y Takahara
- Y Tamura
- Y Tanagida
- Y Tani
- Y Tani
- Y Tominaga
- Y Tominatsu
- Y Tominatsu
- Y Watanabe
- Y Yamasai
- Y Yasukochi
- Y Yasukochi
- Y Yoshida
- Y Yoshida
- Y Yoshida
- Y. Miyake T. Abe, and T. Yamano, in International Symposium on Oxidases and Related Redox Systems
- YA Sharonov
- YA Sharonov
- YA Sharonov
- YE Erokhin
- YJ Kang
- YK Turakulov
- YK Turakulov
- YK Yip
- YP Lin
- YP Meyer
- YP Meyer
- YP Meyer
- YP Myer
- YS Choong
- YS Choong
- YV Peive
- YV Peive
- YV Pieve
- YV Shtamm
- YY Vasilev
- YYH Chao
- Z Bradic
- Z Gasyna
- Z Vogel
- Z Zak
- Publication venue
- 'Springer Science and Business Media LLC'
- Publication date
- 01/01/1984
- Field of study